Publications

2024

Protocol for optical, aqueous-based clearing of murine tissues using EZ Clear

STAR Protocols

Taeyong Ahn, Gabrielle E Largoza, Julia Younis; RE-JOIN Consortium; Mary E Dickinson, Chih-Wei Hsu, Joshua D Wythe

PMID: 38704833 / PMCID: PMC11089399 / DOI: 10.1016/j.xpro.2024.103053

2023

Three-dimensional microCT imaging of mouse heart development from early post-implantation to late fetal stages

Mammalian Genome

Nanbing Li-Villarreal, Tara L Rasmussen, Audrey E Christiansen, Mary E Dickinson, Chih-Wei Hsu

PMID: 36595063 / PMCID: PMC10290591 / DOI: 10.1007/s00335-022-09976-7

Comparative embryology of Delphinapterus leucas (beluga whale), Balaena mysticetus (bowhead whale), and Stenella attenuata (pan-tropical spotted dolphin) (Cetacea: Mammalia)

Journal of Morphology

Lia Gavazzi, Lisa N. Cooper, Sharon Usip, Robert Suydam, Raphaela Stimmelmayr, John C. George, Greg O'Corry-Crowe, Chih-Wei Hsu, Johannes Thewissen

PMID: 36538588 / PMCID: PMC10107513 / DOI: 10.1002/jmor.21543

Rewired m6A epitranscriptomic networks link mutant p53 to neoplastic transformation

Nature Communications

An Xu, Mo Liu, Mo-Fan Huang, Yang Zhang, Ruifeng Hu, Julian A. Gingold, Ying Liu, Dandan Zhu, Chian-Shiu Chien, Wei-Chen Wang, Zian Liao, Fei Yuan, Chih-Wei Hsu, Jian Tu, Yao Yu, Taylor Rosen, Feng Xiong, Peilin Jia, Yi-Ping Yang, Danielle A. Bazer, Ya-Wen Chen, Wenbo Li, Chad D. Huff, Jay-Jiguang Zhu, Francesca Aguilo, Shih-Hwa Chiou, Nathan C. Boles, Chien-Chen Lai, Mien-Chie Hung, Zhongming Zhao, Eric L. Van Nostrand, Ruiying Zhao, Dung-Fang Lee

PMID: 36973285 / PMCID: PMC10042811 / DOI: 10.1038/s41467-023-37398-9

2022

Mendelian gene identification through mouse embryo viability screening

Genome Medicine

Pilar Cacheiro, Carl Henrik Westerberg, Jesse Mager, Mary E Dickinson, Lauryl M J Nutter, Violeta Muñoz-Fuentes, Chih-Wei Hsu, Ignatia B Van den Veyver, Ann M Flenniken, Colin McKerlie, Stephen A Murray, Lydia Teboul, Jason D Heaney, K C Kent Lloyd, Louise Lanoue, Robert E Braun, Jacqueline K White, Amie K Creighton, Valerie Laurin, Ruolin Guo, Dawei Qu, Sara Wells, James Cleak, Rosie Bunton-Stasyshyn, Michelle Stewart, Jackie Harrisson, Jeremy Mason, Hamed Haseli Mashhadi, Helen Parkinson, Ann-Marie Mallon; International Mouse Phenotyping Consortium; Genomics England Research Consortium; Damian Smedley

PMID: 36229886 / PMCID: PMC9563108 / DOI: 10.1186/s13073-022-01118-7

EZ Clear for simple, rapid, and robust mouse whole organ clearing

eLife

Chih-Wei Hsu, Juan Cerda 3rd, Jason M Kirk, Williamson D Turner, Tara L Rasmussen, Carlos P Flores Suarez, Mary E Dickinson, Joshua D Wythe

PMID: 36218247 / PMCID: PMC9555867 / DOI: 10.7554/eLife.77419

Extensive identification of genes involved in congenital and structural heart disorders and cardiomyopathy

Nature Cardiovascular Research

Nadine Spielmann, Gregor Miller, Tudor I. Oprea, Chih-Wei Hsu, Gisela Fobo, Goar Frishman, Corinna Montrone, Hamed Haseli Mashhadi, Jeremy Mason, Violeta Munoz Fuentes, Stefanie Leuchtenberger, Andreas Ruepp, Matias Wagner, Dominik S. Westphal, Cordula Wolf, Agnes Görlach, Adrián Sanz-Moreno, Yi-Li Cho, Raffaele Teperino, Stefan Brandmaier, Sapna Sharma, Isabella Rikarda Galter, Manuela A. Östereicher, Lilly Zapf, Philipp Mayer-Kuckuk, Jan Rozman, Lydia Teboul, Rosie K. A. Bunton-Stasyshyn, Heather Cater, Michelle Stewart, Skevoulla Christou, Henrik Westerberg, Amelia M. Willett, Janine M. Wotton, Willson B. Roper, Audrey E. Christiansen, Christopher S. Ward, Jason D. Heaney, Corey L. Reynolds, Jan Prochazka, Lynette Bower, David Clary, Mohammed Selloum, Ghina Bou About, Olivia Wendling, Hugues Jacobs, Sophie Leblanc, Hamid Meziane, Tania Sorg, Enrique Audain, Arthur Gilly, Nigel W. Rayner, IMPC consortium, Genomics England Research Consortium, Marc-Phillip Hitz, Eleftheria Zeggini, Eckhard Wolf, Radislav Sedlacek, Steven A. Murray, Karen L. Svenson, Robert E. Braun, Jaqueline K. White, Lois Kelsey, Xiang Gao, Toshihiko Shiroishi, Ying Xu, Je Kyung Seong, Fabio Mammano, Glauco P. Tocchini-Valentini, Arthur L. Beaudet, Terrence F. Meehan, Helen Parkinson, Damian Smedley, Ann-Marie Mallon, Sara E. Wells, Harald Grallert, Wolfgang Wurst, Susan Marschall, Helmut Fuchs, Steve D. M. Brown, Ann M. Flenniken, Lauryl M. J. Nutter, Colin McKerlie, Yann Herault, K. C. Kent Lloyd, Mary E. Dickinson, Valerie Gailus-Durner, Martin Hrabe de Angelis

DOI: 10.1038/s44161-022-00018-8

2020

Mouse models to study the pathophysiology of combined methylmalonic acidemia and homocystinuria, cblC type

Developmental Biology

Tiffany Chern, Annita Achilleos, Xuefei Tong, Chih-Wei Hsu, Leeyean Wong, Ross A. Poché

PMID: 32941884 \ PMCID: PMC7669717 \ DOI: 10.1016/j.ydbio.2020.09.005

A global Slc7a7 knockout mouse model demonstrates characteristic phenotypes of human lysinuric protein intolerance

Human Molecular Genetics

Bridget M Stroup, Ronit Marom, Xiaohui Li, Chih-Wei Hsu, Cheng-Yen Chang, Luan D Truong, Brian Dawson, Ingo Grafe, Yuqing Chen, Ming-Ming Jiang, Denise Lanza, Jennie Rose Green, Qin Sun, J P Barrish, Safa Ani, Audrey E Christiansen, John R Seavitt, Mary E Dickinson, Farrah Kheradmand, Jason D Heaney, Brendan Lee, Lindsay C Burrage

PMID: 32504080 \ PMCID: PMC7399531 \ DOI: 10.1093/hmg/ddaa107

Bioinformatics

Hamed Haselimashhadi, Jeremy C Mason, Violeta Munoz-Fuentes, Federico López-Gómez, Kolawole Babalola, Elif F Acar, Vivek Kumar, Jacqui White, Ann M Flenniken, Ruairidh King, Ewan Straiton, John Richard Seavitt, Angelina Gaspero, Arturo Garza, Audrey E Christianson, Chih-Wei Hsu, Corey L Reynolds, Denise G Lanza, Isabel Lorenzo, Jennie R Green, Juan J Gallegos, Ritu Bohat, Rodney C Samaco, Surabi Veeraragavan, Jong Kyoung Kim, Gregor Miller, Helmult Fuchs, Lillian Garrett, Lore Becker, Yeon Kyung Kang, David Clary, Soo Young Cho, Masaru Tamura, Nobuhiko Tanaka, Kyung Dong Soo, Alexandr Bezginov, Ghina Bou About, Marie-France Champy, Laurent Vasseur, Sophie Leblanc, Hamid Meziane, Mohammed Selloum, Patrick T Reilly, Nadine Spielmann, Holger Maier, Valerie Gailus-Durner, Tania Sorg, Masuya Hiroshi, Obata Yuichi, Jason D Heaney, Mary E Dickinson, Wurst Wolfgang, Glauco P Tocchini-Valentini, Kevin C Kent Lloyd, Colin McKerlie, Je Kyung Seong, Herault Yann, Martin Hrabé de Angelis, Steve D M Brown, Damian Smedley, Paul Flicek, Ann-Marie Mallon, Helen Parkinson, Terrence F Meehan

PMID: 31591642 / PMCID: PMC7115897 / DOI: 10.1093/bioinformatics/btz744

Soft windowing application to improve analysis of high-throughput phenotyping data

Human and mouse essentiality screens as a resource for disease gene discovery

Nature Communications

Pilar Cacheiro, Violeta Muñoz-Fuentes, Stephen A. Murray, Mary E. Dickinson, Maja Bucan, Lauryl M. J. Nutter, Kevin A. Peterson, Hamed Haselimashhadi, Ann M. Flenniken, Hugh Morgan, Henrik Westerberg, Tomasz Konopka, Chih-Wei Hsu, Audrey Christiansen, Denise G. Lanza, Arthur L. Beaudet, Jason D. Heaney, Helmut Fuchs, Valerie Gailus-Durner, Tania Sorg, Jan Prochazka, Vendula Novosadova, Christopher J. Lelliott, Hannah Wardle-Jones, Sara Wells, Lydia Teboul, Heather Cater, Michelle Stewart, Tertius Hough, Wolfgang Wurst, Radislav Sedlacek, David J. Adams, John R. Seavitt, Glauco Tocchini-Valentini, Fabio Mammano, Robert E. Braun, Colin McKerlie, Yann Herault, Martin Hrabě de Angelis, Ann-Marie Mallon, K. C.  Kent Lloyd, Steve D. M. Brown, Helen Parkinson, Terrence F. Meehan, Damian Smedley, The Genomics England Research Consortium & The International Mouse Phenotyping Consortium

PMID: 32005800 / PMCID: PMC6994715 / DOI: 10.1038/s41467-020-14284-2

2019

High Resolution Imaging of Mouse Embryos and Neonates with X-Ray Micro-Computed Tomography

Current Protocols in Mouse Biology

Chih-Wei Hsu, Sowmya Kalaga, Uchechukwu Akoma, Tara L. Rasmussen, Audrey E. Christiansen, Mary E. Dickinson

PMID: 31195428 \ PMCID: PMC6594408 \ DOI: 10.1002/cpmo.63

New models for human disease from the International Mouse Phenotyping Consortium

Mammalian Genome

Pilar Cacheiro, Melissa A Haendel, Damian Smedley; International Mouse Phenotyping Consortium and the Monarch Initiative

PMID: 31127358 / PMCID: PMC6606664 / DOI: 10.1007/s00335-019-09804-5

2018

The effects of reduced hemodynamic loading on morphogenesis of the mouse embryonic heart

Developmental Biology

Tanner G. Hoog, Samantha J. Fredrickson, Chih-Wei Hsu, Steven M. Senger, Mary E. Dickinson, Ryan S. Udan

PMID: 30012423 / DOI: 10.1016/j.ydbio.2018.07.007

Rapid and Integrative Discovery of Retina Regulatory Molecules

Cell Reports

Nicholas E Albrecht, Jonathan Alevy, Danye Jiang, Courtney A Burger, Brian I Liu, Fenge Li, Julia Wang, Seon-Young Kim, Chih-Wei Hsu, Sowmya Kalaga, Uchechukwu Udensi, Chinwe Asomugha, Ritu Bohat, Angelina Gaspero, Monica J Justice, Peter D Westenskow, Shinya Yamamoto, John R Seavitt, Arthur L Beaudet, Mary E Dickinson, Melanie A Samuel

PMID: 30157441 / PMCID: PMC6170014 / DOI: 10.1016/j.celrep.2018.07.090

The role of FREM2 and FRAS1 in the development of congenital diaphragmatic hernia

Human Molecular Genetics

Valerie K Jordan, Tyler F Beck, Andres Hernandez-Garcia, Peter N Kundert, Bum-Jun Kim, Shalini N Jhangiani, Tomasz Gambin, Molly Starkovich, Jaya Punetha, Ingrid S Paine, Jennifer E Posey, Alexander H Li, Donna Muzny, Chih-Wei Hsu, Amber J Lashua, Xin Sun, Caraciolo J Fernandes, Mary E Dickinson, Kevin P Lally, Richard A Gibbs, Eric Boerwinkle, James R Lupski, Daryl A Scott

PMID: 29618029 / PMCID: PMC5985720 / DOI: 10.1093/hmg/ddy110

2017

Loss of Apela Peptide in Mice Causes Low Penetrance Embryonic Lethality and Defects in Early Mesodermal Derivatives

Cell Reports

Laina Freyer, Chih-Wei Hsu, Sonja Nowotschin, Andrea Pauli, Junji Ishida, Keiji Kuba, Akiyoshi Fukamizu, Alexander F Schier, Pamela A Hoodless, Mary E Dickinson, Anna-Katerina Hadjantonakis

PMID: 28854362 / PMCID: PMC5580402 / DOI: 10.1016/j.celrep.2017.08.014

Tubulogenesis of co-cultured human iPS-derived endothelial cells and human mesenchymal stem cells in fibrin and gelatin methacrylate gels

Biomaterial Science

Gisele A Calderon, Patricia Thai, Chih-Wei Hsu, Bagrat Grigoryan, Sydney M Gibson, Mary E Dickinson, Jordan S Miller

PMID: 28661522 / DOI: 10.1039/c7bm00223h

2016

Three-dimensional microCT imaging of mouse development from early post-implantation to early postnatal stages

Developmental Biology

Chih-Wei Hsu, Leeyean Wong, Tara L Rasmussen, Sowmya Kalaga, Melissa L McElwee, Lance C Keith, Ritu Bohat, John R Seavitt, Arthur L Beaudet, Mary E Dickinson

PMID: 27671873 / PMCID: PMC5405732 / DOI: 10.1016/j.ydbio.2016.09.011

High-throughput discovery of novel developmental phenotypes

Nature

Mary E Dickinson, Ann M Flenniken, Xiao Ji, Lydia Teboul, Michael D Wong, Jacqueline K White, Terrence F Meehan, Wolfgang J Weninger, Henrik Westerberg, Hibret Adissu, Candice N Baker, Lynette Bower, James M Brown, L Brianna Caddle, Francesco Chiani, Dave Clary, James Cleak, Mark J Daly, James M Denegre, Brendan Doe, Mary E Dolan, Sarah M Edie, Helmut Fuchs, Valerie Gailus-Durner, Antonella Galli, Alessia Gambadoro, Juan Gallegos, Shiying Guo, Neil R Horner, Chih-Wei Hsu, Sara J Johnson, Sowmya Kalaga, Lance C Keith, Louise Lanoue, Thomas N Lawson, Monkol Lek, Manuel Mark, Susan Marschall, Jeremy Mason, Melissa L McElwee, Susan Newbigging, Lauryl M J Nutter, Kevin A Peterson, Ramiro Ramirez-Solis, Douglas J Rowland, Edward Ryder, Kaitlin E Samocha, John R Seavitt, Mohammed Selloum, Zsombor Szoke-Kovacs, Masaru Tamura, Amanda G Trainor, Ilinca Tudose, Shigeharu Wakana, Jonathan Warren, Olivia Wendling, David B West, Leeyean Wong, Atsushi Yoshiki; International Mouse Phenotyping Consortium; Jackson Laboratory; Infrastructure Nationale PHENOMIN, Institut Clinique de la Souris (ICS); Charles River Laboratories; MRC Harwell; Toronto Centre for Phenogenomics; Wellcome Trust Sanger Institute; RIKEN BioResource Center; Daniel G MacArthur, Glauco P Tocchini-Valentini, Xiang Gao, Paul Flicek, Allan Bradley, William C Skarnes, Monica J Justice, Helen E Parkinson, Mark Moore, Sara Wells, Robert E Braun, Karen L Svenson, Martin Hrabe de Angelis, Yann Herault, Tim Mohun, Ann-Marie Mallon, R Mark Henkelman, Steve D M Brown, David J Adams, K C Kent Lloyd, Colin McKerlie, Arthur L Beaudet, Maja Bućan, Stephen A Murray

PMID: 27626380 / PMCID: PMC5295821 / DOI: 10.1038/nature19356

Lineage tracing of Sox2-expressing progenitor cells in the mouse inner ear reveals a broad contribution to non-sensory tissues and insights into the origin of the organ of Corti

Developmental Biology

Rende Gu, Rogers M Brown 2nd, Chih-Wei Hsu, Tiantian Cai, Alyssa L Crowder, Victor G Piazza, Tegy J Vadakkan, Mary E Dickinson, Andrew K Groves

PMID: 27090805 / PMCID: PMC4875846 / DOI: 10.1016/j.ydbio.2016.03.027

RONIN Is an Essential Transcriptional Regulator of Genes Required for Mitochondrial Function in the Developing Retina

Cell Reports

Ross A Poché, Min Zhang, Elda M Rueda, Xuefei Tong, Melissa L McElwee, Leeyean Wong, Chih-Wei Hsu, Marion Dejosez, Alan R Burns, Donald A Fox, James F Martin, Thomas P Zwaka, Mary E Dickinson

PMID: 26876175 / PMCID: PMC4767647 / DOI: 10.1016/j.celrep.2016.01.039

Yap and Taz play a crucial role in neural crest-derived craniofacial development

Development

Jun Wang, Yang Xiao, Chih-Wei Hsu, Idaliz M Martinez-Traverso, Min Zhang, Yan Bai, Mamoru Ishii, Robert E Maxson, Eric N Olson, Mary E Dickinson, Joshua D Wythe, James F Martin

PMID: 26718006 / PMCID: PMC4760309 / DOI: 10.1242/dev.126920

2015

Improved Angiogenesis in Response to Localized Delivery of Macrophage-Recruiting Molecules

PLoS One

Chih-Wei Hsu, Ross A Poché, Jennifer E Saik, Saniya Ali, Shang Wang, Nejla Yosef, Gisele A Calderon, Larry Scott Jr, Tegy J Vadakkan, Irina V Larina, Jennifer L West, Mary E Dickinson

PMID: 26132702 / PMCID: PMC4489184 / DOI: 10.1371/journal.pone.0131643

Macrophages engulf endothelial cell membrane particles preceding pupillary membrane capillary regression

Developmental Biology

Ross A Poché, Chih-Wei Hsu, Melissa L McElwee, Alan R Burns, Mary E Dickinson

PMID: 25912686 / PMCID: PMC4469537 / DOI: 10.1016/j.ydbio.2015.03.017

2014

Quantitative imaging of cell dynamics in mouse embryos using light-sheet microscopy

Development

Ryan S Udan, Victor G Piazza, Chih-Wei Hsu, Anna-Katerina Hadjantonakis, Mary E Dickinson

PMID: 25344073 / PMCID: PMC4302910 / DOI: 10.1242/dev.111021

2011

Visible light photoinitiation of mesenchymal stem cell-laden bioresponsive hydrogels

European Cells & Materials

Chelsea S Bahney, T.J. Lujan, Chih-Wei Hsu, M Bottling, Jennifer L West, Brian Johnstone

PMID: 21761391 / PMCID: PMC5050040 / DOI: 10.22203/ecm.v022a04

Cathepsin K-sensitive poly(ethylene glycol) hydrogels for degradation in response to bone resorption

Journal of Biomedical Materials Research, PART A

Chih-Wei Hsu, Ronke M Olabisi, Elizabeth A Olmsted-Davis, Alan R Davis, Jennifer L West

PMID: 21523904 / DOI: 10.1002/jbm.a.33076

A bioresponsive hydrogel tuned to chondrogenesis of human mesenchymal stem cells

FASEB Journal

Chelsea S Bahney, Chih-Wei Hsu, Jung U Yoo, Jennifer L West, Brian Johnstone

PMID: 21282205 / PMCID: PMC6188228 / DOI: 10.1096/fj.10-165514

2004 - 2007

Increased expression of extracellular matrix proteins in rapid atrial pacing-induced atrial fibrillation

Heart Rhythm

Chih-Sheng Lin, Ling-Ping Lai, Jiunn-Lee Lin, Yu-Ling Sun, Chih-Wei Hsu, Chien-Lung Chen, Simon J T Mao, Shoei K Stephen Huang

PMID: 17599682 / DOI: 10.1016/j.hrthm.2007.03.034

Differentially transcribed genes in skeletal muscle of Duroc and Taoyuan pigs

Journal of Animal Science

Chih-Sheng Lin, Chih-Wei Hsu

PMID: 16100062 / DOI: 10.2527/2005.8392075x

Gene transfections with p53 and p21 inhibit cell proliferation, collagen type I, leukemia inhibitory factor, and tumor necrosis factor-alpha expression in leiomyoma cells

FASEB Journal

Yao-Yuan Hsieh, Chi-Chen Chang, Chih-Wei Hsu, Chich-Sheng Lin

PMID: 15193492 / DOI: 10.1016/j.fertnstert.2004.02.062